Heterotopic Gastrointestinal Cyst of the Tongue: Case Report

혀에 발생한 이소성 구강 위장관 낭종: 증례보고

  • Kim, So-Mi (Department of Oral and Maxillofacial Surgery, College of Dentistry, Yonsei University) ;
  • Kil, Tae-Joon (Department of Oral and Maxillofacial Surgery, College of Dentistry, Yonsei University) ;
  • Hahm, Tae-Hoon (Department of Oral and Maxillofacial Surgery, College of Dentistry, Yonsei University) ;
  • Kim, Hyun-Sil (Department of Oral and Maxillofacial Pathology, College of Dentistry, Yonsei University) ;
  • Yi, Choong-Kook (Department of Oral and Maxillofacial Surgery, College of Dentistry, Yonsei University) ;
  • Cha, In-Ho (Department of Oral and Maxillofacial Pathology, College of Dentistry, Yonsei University)
  • 김소미 (연세대학교 치과대학 구강악안면외과학교실) ;
  • 길태준 (연세대학교 치과대학 구강악안면외과학교실) ;
  • 함태훈 (연세대학교 치과대학 구강악안면외과학교실) ;
  • 김현실 (연세대학교 치과대학 구강병리학교실) ;
  • 이충국 (연세대학교 치과대학 구강악안면외과학교실) ;
  • 차인호 (연세대학교 치과대학 구강병리학교실)
  • Received : 2010.09.20
  • Accepted : 2010.10.05
  • Published : 2011.01.31

Abstract

Gastrointestinal cyst found within the oral cavity has been reported as a rare occurrence with less than 40 cases. The tongue is the preferred site with almost 60% of cysts occurring within oral cavity. The cyst usually shows an asymptomatic swelling in the floor of the mouth, about 30% of affected individuals have symptoms related to difficulties with feeding, swallowing and respiration. The histopathologic features of the cyst vary with respect to the type of epithelium lining; gastric, squamous, intestinal and respiratory epithelium. The pathogenesis is not known, but it may be related to entrapment of undifferentiated endoderm within oral cavity during early fetal development. In this article, we report a case of a gastrointestinal cyst of the tongue in a 16-month-old girl.

Keywords

References

  1. Wetmore RF, Bartlett SP, Papsin B, Todd NW. Heterotopic gastric mucosa of the oral cavity: a rare entity. Int J Pediatr Otorhinolaryngol 2002;66:139-42. https://doi.org/10.1016/S0165-5876(02)00236-7
  2. Foderl O. Uber einen fall von congenitaler ranula glandulae nuhni. Archiv fur Klinische Chirurgie 1895;49:530-40.
  3. Morgan WE, Jones JK, Flaitz CM, Hicks MJ. Congenital heterotopic gastrointestinal cyst of the oral cavity in a neonate: case report and review of literature. Int J Pediatr Otorhinolaryngol 1996;36:69-77. https://doi.org/10.1016/0165-5876(96)01331-6
  4. Barnes L. Surgical pathology of the head and neck. New York: Marcel Decker; 1985. p.1278-95.
  5. Quinn JH, Robinson WC. Multiple congenital cysts of the floor of the mouth in a newborn infant. Oral Surg Oral Med Oral Pathol 1965;20:1-5. https://doi.org/10.1016/0030-4220(65)90258-6
  6. Willis RA. Some unusual heterotopies. Br Med J 1968;3: 267-72. https://doi.org/10.1136/bmj.3.5613.267
  7. Batsakis JG, el-Naggar AK, Hicks MJ. Epithelial choristomas and teratomas of the tongue. Ann Otol Rhinol Laryngol 1993;102:567-9. https://doi.org/10.1177/000348949310200715
  8. Bite U, Cramer HM. Mixed heterotopic gastrointestinal and respiratory cyst of the lip: case report and review of the literature. Plast Reconstr Surg 1992;90:1068-72. https://doi.org/10.1097/00006534-199212000-00021
  9. Daley TD, Wysocki GP, Lovas GL, Smout MS. Heterotopic gastric cyst of the oral cavity. Head Neck Surg 1984;7: 168-71. https://doi.org/10.1002/hed.2890070212
  10. Lipsett J, Sparnon AL, Byard RW. Embryogenesis of enterocystomas- enteric duplication cysts of the tongue. Oral Surg Oral Med Oral Pathol 1993;75:626-30. https://doi.org/10.1016/0030-4220(93)90238-Y
  11. Gruskin P, Landolfe FR. Heterotopic gastric mucosa of the tongue. Arch Pathol 1972;94:184-6.
  12. Woolgar JA, Smith AJ. Heterotopic gastrointestinal cyst of oral cavity: a developmental lesion? Oral Surg Oral Med Oral Pathol 1988;66:223-5. https://doi.org/10.1016/0030-4220(88)90097-7