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Bilateral Checkrein Deformities of the Hallux Following Intramuscular Sarcoidosis: A Case Report

근육 내 사르코이드증 후 발생한 양측 무지의 체크레인 변형: 증례 보고

  • Min Gyu Kyung (Department of Orthopedic Surgery, Kyung Hee University Hospital at Gangdong) ;
  • Sangyun Yun (Department of Orthopedic Surgery, Seoul National University Hospital) ;
  • Dong Yeon Lee (Department of Orthopedic Surgery, Seoul National University College of Medicine)
  • 경민규 (강동경희대학교병원 정형외과) ;
  • 윤상윤 (서울대학교병원 정형외과) ;
  • 이동연 (서울대학교 의과대학 정형외과학교실)
  • Received : 2024.03.21
  • Accepted : 2024.04.04
  • Published : 2024.06.15

Abstract

This report presents a unique case of checkrein deformities in both halluces following isolated intramuscular sarcoidosis, a rare occurrence given the infrequent musculoskeletal involvement in sarcoidosis. Typically resulting from flexor hallucis longus tendon entrapment by scar tissue post-trauma, the checkrein deformity reported in this paper presented with unusual metatarsophalangeal joint flexion and interphalangeal joint extension during ankle dorsiflexion. A 49-year-old woman with a history of intramuscular sarcoidosis presented with a great toe deformity and discomfort while wearing shoes, leading to a diagnosis of dynamic deformity, possibly attributed to tendon tethering by sarcoidosis. Surgical treatments, including abductor hallucis muscle intratendinous tenotomy, flexor hallucis longus Z-plasty lengthening, Weil osteotomy, and Kirschner wire fixation, significantly improved the functional scores and patient discomfort. This report underscores the importance of recognizing dynamic deformities and the potential for rare diseases, such as sarcoidosis, to cause such conditions, highlighting the need for careful diagnosis and tailored surgical intervention for atypical checkrein deformities.

Keywords

Acknowledgement

This work was supported by Basic Science Research Program through the National Research Foundation of Korea (NRF) funded by the Ministry of Education (NRF-2016R1D1A1B02009379).

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