Journal of Korean Foot and Ankle Society (대한족부족관절학회지)

Korean Foot & Ankle Society (대한족부족관절학회)
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Melorheostosis with Synovial Chondromatosis of the Foot: A Report of Two Cases

족부에 발생한 활막 연골종증을 동반한 유선상 과오종: 2예 보고

  • Lee, Chae Chil (Department of Orthopedic Surgery, Ulsan University Hospital, University of Ulsan College of Medicine) ;
  • Kim, Sang Woo (Department of Orthopedic Surgery, Ulsan University Hospital, University of Ulsan College of Medicine) ;
  • Choi, Hye Jeong (Department of Pathology, Ulsan University Hospital, University of Ulsan College of Medicine) ;
  • Hwang, Il Yeong (Department of Orthopedic Surgery, Ulsan University Hospital, University of Ulsan College of Medicine) ;
  • Kim, Min Seok (Department of Orthopedic Surgery, Ulsan University Hospital, University of Ulsan College of Medicine)
  • 이채칠 (울산대학교 의과대학 울산대학교병원 정형외과학교실) ;
  • 김상우 (울산대학교 의과대학 울산대학교병원 정형외과학교실) ;
  • 최혜정 (울산대학교 의과대학 울산대학교병원 병리학교실) ;
  • 황일영 (울산대학교 의과대학 울산대학교병원 정형외과학교실) ;
  • 김민석 (울산대학교 의과대학 울산대학교병원 정형외과학교실)
  • Received : 2015.05.04
  • Accepted : 2015.11.11
  • Published : 2015.12.15
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Abstract

Melorheostosis is a rare disease, belonging to the sclerotic bone dysplasia group. Initially described by Leri and Joanny in 1922, its etiology remains unknown. Onset is usually insidious, with deformity of the extremity, pain, limb stiffness, and limitation of motion in the joints. The typical radiographic appearance consists of irregular hyperostotic changes of the cortex, resembling melted wax dripping down one side of a candle. Treatment is usually symptomatic and conservative; however, conservative treatment is unsatisfactory due to functional issues when involving the distal extremity. We report on two cases of melorheostosis with synovial chondromatosis of the foot treated by mass excision.

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References

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