Journal of the Korean Association of Oral and Maxillofacial Surgeons

The Korean Association of Oral and Maxillofacial Surgeons (대한구강악안면외과학회)
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Keratoameloblastoma of the maxilla: a case report

상악골에 발생한 각화법랑모세포종: 증례보고

  • Won, Ji-Hoon (Department of Oral and Maxillofacial Surgery, College of Dentistry, Yonsei University) ;
  • Na, Hye-Young (Department of Oral and Maxillofacial Surgery, College of Dentistry, Yonsei University) ;
  • Kim, Hyun-Sil (Department of Oral Cancer Research Institute, College of Dentistry, Yonsei University) ;
  • Kim, Jin (Department of Oral Cancer Research Institute, College of Dentistry, Yonsei University) ;
  • Nam, Woong (Department of Oral and Maxillofacial Surgery, College of Dentistry, Yonsei University) ;
  • Cha, In-Ho (Department of Oral and Maxillofacial Surgery, College of Dentistry, Yonsei University) ;
  • Kim, Hyung-Jun (Department of Oral and Maxillofacial Surgery, College of Dentistry, Yonsei University)
  • 원지훈 (연세대학교 치과대학 구강악안면외과학교실) ;
  • 나혜영 (연세대학교 치과대학 구강악안면외과학교실) ;
  • 김현실 (연세대학교 치과대학 구강종양연구소) ;
  • 김진 (연세대학교 치과대학 구강종양연구소) ;
  • 남웅 (연세대학교 치과대학 구강악안면외과학교실) ;
  • 차인호 (연세대학교 치과대학 구강악안면외과학교실) ;
  • 김형준 (연세대학교 치과대학 구강악안면외과학교실)
  • Received : 2011.07.05
  • Accepted : 2011.10.12
  • Published : 2011.12.31
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Abstract

A keratoameloblastoma is a histologically variant of the ameloblastoma group, which varies in size and contains keratin material in the fibrous connective tissue among cystic lesions. A keratoameloblastoma is a rare disease with only 13 cases reported in the literature since Pindborg's first report in 1970. A 41-year-old man visited, complaining of pus discharged from the right maxilla. He had been diagnosed with an odontogenic keratocyst and was treated with cyst enucleation in the past. The clinical and radiology examination found evidence of recurrence and finally diagnosed him with keratoameloblastoma after enucleation and biopsy. This report discusses the clinical, radiological and histological characteristics of keratoameloblastoma and its treatment. In addition, we report another case of keratoameloblastoma that had transformed from an odontogenic keratocyst.

Keywords

References

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