A Case of Nocturnal Paroxysmal Dystonia: Frontal Lobe Epilepsy and Parasomnias (FLEP) Scale, Polysomnography and Subtraction of Ictal-interictal SPECT Coregistered with MRI (SISCOM) Findings

야간발작성근육긴장이상 1예: 전두엽간질 및 사건수면척도, 수면다원검사, 발작기 및 발작간기 감산 SPECT 소견

  • Kim, Woojun (Department of Neurology, The Catholic University of Korea) ;
  • Oh, Yun-Sang (Department of Neurology, The Catholic University of Korea) ;
  • Yoon, Bora (Department of Neurology, The Catholic University of Korea) ;
  • Kim, Yeong-In (Department of Neurology, The Catholic University of Korea) ;
  • Lee, Kwang-Soo (Department of Neurology, The Catholic University of Korea) ;
  • Kim, Joong-Seok (Department of Neurology, The Catholic University of Korea)
  • 김우준 (가톨릭대학교 의과대학 신경과학교실) ;
  • 오연상 (가톨릭대학교 의과대학 신경과학교실) ;
  • 윤보라 (가톨릭대학교 의과대학 신경과학교실) ;
  • 김영인 (가톨릭대학교 의과대학 신경과학교실) ;
  • 이광수 (가톨릭대학교 의과대학 신경과학교실) ;
  • 김중석 (가톨릭대학교 의과대학 신경과학교실)
  • Received : 2007.12.28
  • Accepted : 2008.02.05
  • Published : 2008.06.30

Abstract

Even though the origin and nature of nocturnal paroxysmal dystonia (NPD) remains unclear, it has been considered as a manifestation of the nocturnal frontal lobe epilepsy. We report a 17-year-old man with abnormal stereotyped movement during sleep. Video-EEG monitoring, ictal SPECT and night polysomnography did not show any evidence of epilepsy. However, the partial response to large dose of carbamazepine and the scoring according to the frontal lobe epilepsy and parasomnias (FLEP) scale suggest his events could be classified as epilepsy. Therefore we think the FLEP scale might be a useful tool for differential diagnosis in a patient presenting NPD.

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