1 Case of Bronchial Leiomyoma with Intralobar Pulmonary Sequestration

폐 격리증을 동반한 기관지내 평활근종 1례

  • Jung, Bo Yong (Department of Internal Medicine, University of Soonchunhyang college of Medicine) ;
  • Kim, Do Hwan (Department of Internal Medicine, University of Soonchunhyang college of Medicine) ;
  • Park, Eun Seo (Department of Internal Medicine, University of Soonchunhyang college of Medicine) ;
  • Han, Seung Hoe (Department of Internal Medicine, University of Soonchunhyang college of Medicine) ;
  • Kim, Young Tong (Department of Radiology, University of Soonchunhyang college of Medicine) ;
  • Oh, Mi Hye (Department of Diagnostic Pathology, University of Soonchunhyang college of Medicine) ;
  • Lee, Seok Yul (Department of Thoracic Surgery, University of Soonchunhyang college of Medicine) ;
  • Choi, Jae Sung (Department of Internal Medicine, University of Soonchunhyang college of Medicine) ;
  • Na, Joo Ock (Department of Internal Medicine, University of Soonchunhyang college of Medicine) ;
  • Seo, Ki Hyun (Department of Internal Medicine, University of Soonchunhyang college of Medicine) ;
  • Kim, Yong Hoon (Department of Internal Medicine, University of Soonchunhyang college of Medicine)
  • 정보용 (순천향대학교 의과대학 내과학교실) ;
  • 김도환 (순천향대학교 의과대학 내과학교실) ;
  • 박은서 (순천향대학교 의과대학 내과학교실) ;
  • 한승효 (순천향대학교 의과대학 내과학교실) ;
  • 김영통 (순천향대학교 의과대학 영상의학교실) ;
  • 오미혜 (순천향대학교 의과대학 진단병리교실) ;
  • 이석열 (순천향대학교 의과대학 흉부외과교실) ;
  • 최재성 (순천향대학교 의과대학 내과학교실) ;
  • 나주옥 (순천향대학교 의과대학 내과학교실) ;
  • 서기현 (순천향대학교 의과대학 내과학교실) ;
  • 김용훈 (순천향대학교 의과대학 내과학교실)
  • Received : 2006.04.18
  • Accepted : 2006.06.07
  • Published : 2006.06.30

Abstract

Both bronchial leiomyoma and pulmonary sequestration are rare conditions, and to the best of our knowledge there are no reports of the two conditions coexisting. We report a female patient with bronchial leiomyoma with acquired pulmonary sequestration who presented with dyspnea, cough and purulent sputum. The patient had been treated for pneumonia at a local medical clinic. but was transferred to our clinic beacausr there was no clinical improvement. A 3-D computed tomography scan revealed a 1.5 cm sized mass near the distal portion of the left main bronchus and an anomalous artery arising from the aorta. The patient showed clinical improvement after a left lower lobectomy and a ligation of the anomalous artery.

기관지 평활근종과 폐 격리증은 두 질환 모두 희귀한 질환으로 같이 동반된 증례는 현재까지 보고된 적은 없다. 저자들은 호흡곤란, 기침, 화농성 객담을 주소로 개인의원에서 폐렴 치료 후 호전 없어 본원으로 전원 후, 흉부 CT 촬영과 기관지내시경에서 좌폐하엽의 허탈을 동반한 좌측 주기관지의 말단부위에 1.5 cm크기의 종괴와 대동맥에서 나오는 이상 동맥을 발견하여 이상 동맥 결찰과 좌하엽 절제술을 시행하여 호전되었던 폐 격리증을 동반한 기관지 평활근종 1 예를 경험하였기에 문헌고찰과 함께 보고하는 바이다.

Keywords

References

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