A Case Report: Surgical Treatment of Pachydermodactyly

지피비대증 환자의 수술적 치료 1예

  • Rhee, Se Whan (Department of Plastic and Reconstructive Surgery, College of Medicine, Hanyang University) ;
  • Ahn, Hee Chang (Department of Plastic and Reconstructive Surgery, College of Medicine, Hanyang University) ;
  • Hwang, Weon Jung (Department of Plastic and Reconstructive Surgery, College of Medicine, Hanyang University) ;
  • Oh, Jung Keun (Department of Plastic and Reconstructive Surgery, College of Medicine, Hanyang University) ;
  • Lee, Chang Woo (Department of Dermatology, College of Medicine, Hanyang University)
  • 이세환 (한양대학교 의과대학 성형외과학교실) ;
  • 안희창 (한양대학교 의과대학 성형외과학교실) ;
  • 황원중 (한양대학교 의과대학 성형외과학교실) ;
  • 오정근 (한양대학교 의과대학 성형외과학교실) ;
  • 이창우 (한양대학교 의과대학 피부과학교실)
  • Received : 2005.09.07
  • Published : 2006.01.10

Abstract

Pachydermodactyly is a rare distinct form of fibromatosis characterized by acquired, asymptomatic dense fibrosis and fibroblastic proliferation around one or more proximal interphalangeal joints. Intralesional triamcinolone injection may be helpful in improving the clinical appearance. A 20-year-old unemployed female patient gave a four years history of progressive swelling of the fingers affecting predominantly the proximal interphalangeal joints of index fingers of left hand and index, middle fingers of right hand. There was no pain and tenderness. Physical examination, complete blood count, antinuclear antibody, rheumatoid factor were unremarkable and radiograph of both hands showed soft tissue swelling only without bony abnormality. We excised the redundant soft tissue from the both sides of proximal interphalangeal joint with longitudinal elliptical fashion. After operation, the fingers of the patient showed marked improvement cosmetically. There were no motor or sensory changes. Pachydermodactyly was first reported in 1996 in Korea. Histologic features include an increased dermal accumulation of collagen and occasionally an increased number of fibroblast. We report for one patient with pachydermodactyly treated with longitudinal elliptical excision and obtained an improvement of clinical appearance.

Keywords

References

  1. Reichert CM, Costa J, Barsky SH, Oaysmith AP, Liotta LA, Enzinger PM, Triche 1]: Pachydermodactyly. Clin Orthap Relat Res 194: 252, 1985
  2. Youn KH, Kim DK: A case of Pachydermodactyly: Korean J Dermatol 34: 459, 1996
  3. Draluck JC, Kopf AW, Hodak E: Pachydermodactyly: First report in a woman. J Am Acad Dermatol 27: 303, 1992 https://doi.org/10.1016/0190-9622(92)70186-J
  4. Curley RK, Hudson PM, Marsden RA: Pachydermodactyly: a rare form of digital fibromatosis-report of four cases. Clin Exp Dermatol 16: 121, 1991 https://doi.org/10.1111/j.1365-2230.1991.tb00321.x
  5. Fleeter TB, Myrie C, Adams JP: Pachyderrnodactyly: a case report and discussion of the pathologic entity. J Hand Surg 9: 764; 1984