Journal of Korean Neurosurgical Society

  • 제37권1호
  • /
  • Pages.63-66
  • /
  • 2005
  • /
  • 2005-3711(pISSN)
  • /
  • 1598-7876(eISSN)
대한신경외과학회 (The Korean Neurosurgical Society)
권호 표지

Currarino Triad

  • Lee, Ho-Jin (Department of Neurosurgery, Seoul Medical Center) ;
  • Kong, Min-Ho (Department of Neurosurgery, Seoul Medical Center) ;
  • Kim, Dong-Seok (Departments of Neurosurgery, Yonsei University College of Medicine) ;
  • Kim, Tae-Sung (Departments of Pathology, Yonsei University College of Medicine)
  • 발행 : 2005.01.31
PDF 다운로드
⟨ 이전 논문 다음 논문 ⟩

초록

The authors report a case of Currarino triad which had a congenital anorectal stenosis associated with a sacral defect and a presacral mass. A 1-year-old female presented with constipation since birth. Neurological deficits were not found on admission. She had had a diverting colostomy due to anorectal stenosis at another hospital before admission. Lumbar X-ray films showed bony defect caudal to the third sacral vertebra. Magnetic resonance image demonstrated a round cystic pelvic mass which was connected with a dural sac via anterior sacral defect. Posterior approach with Intradural removal of the presacral cystic mass was performed and followed by anoplasty by a pediatric surgeon. The cystic mass was verified histologically as mature teratoma with cystic change. Postoperatively, the urinary function and bowel movement remained intact. Currarino triad should be suspected and evaluated physically and radiographically in a case of congenital anorectal stenosis. Prompt recognition and close cooperation between pediatric surgeons and neurosurgeons is advisable to ensure adequate surgical treatment.

키워드

참고문헌

  1. Aaronson I : Anterior sacral meningocele, anal canal duplication cyst and covered anus occuring in one family. J Pediatr Surg 5 : 559- 563, 1970 https://doi.org/10.1016/0022-3468(70)90522-1
  2. Anderson FM, Burke BL : Anterior sacral meningocele : A presentation of three cases. JAMA 237 : 39, 1977 https://doi.org/10.1001/jama.237.1.39
  3. Ashcraft KW, Holder TM : Hereditary presacral teratoma. J Pediatr Surg 9 : 691-697, 1974 https://doi.org/10.1016/0022-3468(74)90107-9
  4. Cohn J, Bay-Nielsen E : Hereditary defect of the sacrum and coccyx with anterior sacral meningocele. Acta Pediatr Scand 58 : 268-274, 1969 https://doi.org/10.1111/j.1651-2227.1969.tb04716.x
  5. Currarino G, Coln D, Votteler T : Triad of anorectal, sacral, and presacral anomalies. AJR 137 : 395-398, 1981 https://doi.org/10.2214/ajr.137.2.395
  6. Heij HA, Moorman-Voestermans CGM, Vos A, Kneepkens CMF : Triad of anorectal stenosis, sacral anomaly and presacral mass : A remediable cause of severe constipation. Br J Surg 77 : 102-104, 1990 https://doi.org/10.1002/bjs.1800770135
  7. Karrer FM, Flannery AM, Nelson JMD, McLone DG, Raffensperger JG : Anorectal malformations : Evaluation of associated spinal dysraphic syndromes. J Pediatr Surg 23 : 45-48, 1988 https://doi.org/10.1016/S0022-3468(88)80538-4
  8. Kim HS, Park CW, Bak KH, Lee U : Presacral mass in Currarino Triad. J Korean Neurosurg Soc 22 : 905-911, 1993
  9. Lee RA, Symmonds RE : Presacral tumors in the female : clinical presentation, surgical management, and results. Obstet Gynecol 71 : 216-221, 1988
  10. Lee SC, Chun YS, Jung SE, Park KW, Kim WK : Currarino triad : Anorectal malformation, sacral bony abnormality, and presacral mass. A reviews of 11 cases. J Pediatr Surg 32 : 58-61, 1997 https://doi.org/10.1016/S0022-3468(97)90094-4
  11. Malangoni MA, Grosfeld JL, Ballantine TVN, Kleiman M : Congenital rectal stenosis : a sign of presacral pathologic condition. Pediatircs 62 : 584-587, 1978
  12. Park KW, Kim JT, Kim WK : The complex of cogenital anomalies including anorectal malformation, sacral bony abnormalities, and presacral mass. J Korean Surg Soc 31 : 783-788, 1986
  13. Shaker IJ, Lanier VC, Amoury RA : Congenital anal stenosis with anterior sacral meningocele. J Pediatr Surg 6 : 177, 1971 https://doi.org/10.1016/0022-3468(71)90315-0
  14. Stewart RJ, Humphreys WG, Parks TG : The presentation and management of presacral tumours. Br J Surg 73 : 153-155, 1986 https://doi.org/10.1002/bjs.1800730227
  15. Tsuchida Y, Watanasupt W, Nakajo T : Anorectal malformations associated with a presacral tumor and sacral defect. Pediatr Surg Int 4 : 398-402, 1989 https://doi.org/10.1007/BF00169699
  16. Werner JL, Taybi H : Presacral masses in childhood. AJR 109 : 403- 410, 1970 https://doi.org/10.2214/ajr.109.2.403
  17. Yates VD, Wilroy RS, Whitington GL : Anterior sacral defects : an autosomal dominantly inherited condition. J Pediatr 102 : 239-242, 1983 https://doi.org/10.1016/S0022-3476(83)80528-9